Muerte perinatal por atresia laríngea: reporte de caso


Authors

  • Lucy Lorena Bravo Luna Universidad del Cauca
  • Blanca Viviana Fajardo-Idrobo Universidad del Cauca

DOI:

https://doi.org/10.22517/25395203.25272

Keywords:

Larynx, Laryngeal Diseases, Airway Obstruction, Perinatal Death, Congenital Abnormalities, Autopsy.

Abstract

Laryngeal atresia is a congenital malformation of the airway, which occurs due to the lack of recanalization of the laryngeal lumen during embryogenesis. The detection of characteristic sonographic features during pregnancy is required to consider this diagnosis. In this article we present the case of a 39.2-week gestation with poor prenatal controls and a single late gestational ultrasound that did not report abnormalities. At birth, the fetus was non-vigorous and hypotonic, with poor respiratory effort, oral cyanosis and Apgar scores of 4-4-0, for which it underwent resuscitation maneuvers with great difficulty in achieving ventilation and multiple failed endotracheal intubation attempts, although the medical staff indicates that despite identifying the vocal cords, it was impossible for them to pass the tube. Finally the newborn dies. Suspecting a malformation in the upper respiratory tract, request the pathology service to perform a clinical autopsy to confirm the cause of death.

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Author Biographies

Lucy Lorena Bravo Luna, Universidad del Cauca

Médica Patóloga

Blanca Viviana Fajardo-Idrobo, Universidad del Cauca

Médica Patóloga

References

​Landry AM, Rutter MJ. Airway Anomalies. Clin Perinatol [Internet]. 2018; 45(4): 597–607. Available from: https://doi.org/10.1016/j.clp.2018.07.002

Ahmad SM, Soliman AMS. Congenital Anomalies of the Larynx. Otolaryngol Clin North Am. 2007;40(1):177–91.

Fayoux P, Devisme L. Histoanatomical structures of laryngeal atresia: Functional considerations. Laryngoscope. 2020; 130(1): 252–6.

Gosavi M, Kumar L, Ratnakar A, Bannur H. Congenital High Airway Obstruction Syndrome (CHAOS): A perinatal autopsy case report. Pathol Res Pract [Internet]. 2017; 213(2): 170–5. Available from: http://dx.doi.org/10.1016/j.prp.2016.10.009

​Gupta A, Yadav C, Dhruw S, Mishra D, Taori A. Chaos. J Obstet Gynecol India. 2016; 66(3): 202–8.

​Ryan G, Somme S, Crombleholme TM. Airway compromise in the fetus and neonate: Prenatal assessment and perinatal management. Semin Fetal Neonatal Med [Internet]. 2016; 21(4): 230–9. Available from: http://dx.doi.org/10.1016/j.siny.2016.03.002

​Lupariello F, Di Vella G, Botta G. Death Shortly after Delivery Caused by Congenital High Airway Obstruction Syndrome. Fetal Pediatr Pathol [Internet]. 2020; 39(2): 179–83. Available from: https://doi.org/10.1080/15513815.2019.1644688

Lago V, Cortés LM, Seco C. Prenatal diagnosis of congenital high airway obstruction syndrome. Indian J Radiol Imaging [Internet]. 2018; 28(3): 366–8. Available from: https://pubmed.ncbi.nlm.nih.gov/30319217

D’Eufemia MD, Cianci S, Di Meglio F, Di Meglio L, Di Meglio L, Vitale SG, et al. Congenital high airway obstruction syndrome (CHAOS): discussing the role and limits of prenatal diagnosis starting from a single-center case series. J Prenat Med. 2016; 10(1–2): 4.

Lupariello F, Nuzzolese E, Di Vella G. Causes of death shortly after delivery and medical malpractice claims in congenital high airway obstruction syndrome: Review of the literature. Leg Med [Internet]. 2019; 40(August): 61–5. Available from: https://doi.org/10.1016/j.legalmed.2019.07.008

Nolan HR, Gurria J, Peiro JL, Tabbah S, DiazR, Polzin W, et al. Congenital high airway obstruction syndrome (CHAOS): Natural history, prenatal management strategies, and outcomes at a single comprehensive fetal center. J Pediatr Surg [Internet]. 2019; 54(6): 1153–8. Available from: https://doi.org/10.1016/j.jpedsurg.2019.02.034

Chaemsaithong P, Chansoon T, Chanrachakul B, Worawichawong S, Wongwaisayawan S, Promsonthi P. Prenatal Diagnosis and Pathology of Laryngeal Atresia in Congenital High Airway Obstruction Syndrome. Case Rep Radiol. 2012; 1–4.

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Published

2024-03-01

How to Cite

Bravo Luna, L. L., & Fajardo-Idrobo, B. V. (2024). Muerte perinatal por atresia laríngea: reporte de caso. Revista Médica De Risaralda, 29(2), 153–160. https://doi.org/10.22517/25395203.25272